描述一个宫外腺肌瘤（EA）的病例，并回顾文献中的所有EA病例。从1807年到2022年12月，检索Pubmed/MEDLINE、Embase和Google Scholar数据库。收集包括EA组织学诊断的所有研究。我们收集了以下数据：患者年龄、腺肌瘤的大小和位置、子宫内膜异位症和腺肌病的存在、过去的妇科治疗、症状、诊断影像学、手术干预、辅助/补充治疗、相关恶性肿瘤和随访情况。共纳入了67个研究，涉及85名患者。疼痛是最常见的症状（69.5%）。在诊断检查中，超声检查在81例中有60例报道，描述了几个影像学特征。77.6%的患者EA位于盆腔内。卵巢附件是该病最常见的部位（24例，28.2%）。35名患者（35例，41.2%）有子宫内膜异位症或腺肌病的病史。有报道85名患者中有6例（7.1%）进行了子宫组织剖取术。在可获得的数据中，有9名患者（10.6%）发现相关恶性肿瘤。疾病复发发生了两次。 目前尚未在文献中描述EA的特定影像学特征。子宫内膜异位症和腺肌病的病史或子宫组织剖取术可能暗示EA的存在。组织学检查可以确诊并排除恶性转变。© 2023国际妇产科联合会。

To describe a case of extrauterine adenomyoma (EA) and review all the cases of EA in the literature.Pubmed/MEDLINE, Embase, and Google Scholar from 1807 to December 2022. All studies reporting the histologic diagnosis of an EA. We collected the following data: patient's age, size and location of adenomyoma, presence of endometriosis and adenomyosis, past gynecologic treatment, symptoms, diagnostic imaging, surgical intervention, alternative/adjuvant treatment, associated malignancy, and follow up.Sixty-seven studies with 85 patients were included. Pain was the most frequent symptom (69.5%). Among diagnostic examinations, ultrasonography was used in 60 out of 81 reported cases, with several radiologic features described. EA was located inside the pelvis in 77.6% of patients. Adnexa were the most frequent site of the disease (24, 28.2%). History of endometriosis or adenomyosis was described in 35 patients (35, 41.2%). Uterine tissue morcellation was reported in 6 of the 85 patients (7.1%). Associated malignancy was detected in 9 out of 85 patients with available data (10.6%). There were two recurrences of disease.Specific imaging features of EA are yet to be described in the literature. History of endometriosis and adenomyosis or uterine tissue morcellation may be suggestive of EA. Histologic examination can give a definitive diagnosis and exclude malignant transformation.© 2023 International Federation of Gynecology and Obstetrics.